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Hypohidrotic ectodermal dysplasia

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Last updated 2mo ago

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A young boy has sparse hair, conical teeth, and heat intolerance. His mother reports he rarely sweats and had multiple febrile episodes as an infant.

  • XLR: EDA (most common)
  • AR/AD: EDAR, EDARADD
  • Hypohidrosis/anhidrosis → heat intolerance, hyperthermia
  • Hypotrichosis (sparse scalp hair, eyebrows, eyelashes)
  • Hypodontia with conical teeth
  • Characteristic facies: frontal bossing, saddle nose, periorbital darkening
  • Clinical recognition of the triad (hypotrichosis, hypodontia, hypohidrosis) supported by dental imaging showing missing or conical teeth
  • Reduced or absent sweat pores on skin biopsy or sweat-pore counting; sweat testing confirms hypohidrosis
  • Molecular testing (EDA, EDAR, EDARADD) confirms the diagnosis and clarifies inheritance for carrier counseling
  • Temperature regulation: avoid overheating, use cooling measures, and treat fever promptly to prevent hyperthermia
  • Dental rehabilitation with prosthetics, implants, or dentures, often beginning in early childhood
  • Skin and mucosal care for dryness; eye lubrication and management of recurrent respiratory secretions
  • Multidisciplinary follow-up (dental, dermatology, ENT) and genetic counseling for at-risk relatives

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