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A newborn has severe micrognathia causing the tongue to fall back (glossoptosis), resulting in upper airway obstruction. A U-shaped cleft palate is also present.

Heterogeneous

  • Isolated (non-syndromic): often associated with SOX9 regulatory region
  • Syndromic: part of Stickler syndrome, 22q11.2 deletion, others

The sequence:

  1. Micrognathia →
  2. Glossoptosis (tongue falls back) →
  3. U-shaped cleft palate (from tongue preventing palatal shelf fusion)
  4. Upper airway obstruction
  • Clinical diagnosis based on the triad of micrognathia, glossoptosis, and (usually U-shaped) cleft palate with airway obstruction
  • May be identified prenatally by micrognathia on ultrasound; confirmed by postnatal exam
  • Sleep study and airway endoscopy assess the degree of obstruction
  • Evaluate for an underlying syndrome (especially Stickler; also 22q11.2 deletion): ophthalmology exam, hearing evaluation, and genetic testing as indicated
  • Prone positioning
  • May need nasopharyngeal airway, tongue-lip adhesion, or mandibular distraction
  • Always evaluate for underlying syndrome (especially Stickler)

"PierRe-Robin = Respiratory obstruction": the key complication is upper airway obstruction due to glossoptosis.

Pierre-Robin sequence in STickler: think "...PQRST..." (the sequential letters P, Q, R, S, T link Pierre-Robin to STickler syndrome, the most common underlying syndromic cause).

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