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VACTERL (VATER) association

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Last updated 12d ago

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A newborn has a single umbilical artery on routine inspection. Prenatal imaging had shown a missing radius and an "absent stomach bubble." After birth, the infant is unable to feed and a feeding tube cannot pass, indicating esophageal atresia with tracheoesophageal fistula. Echo reveals a VSD; renal ultrasound shows unilateral renal agenesis.

Sporadic in nearly all cases. No single causative gene; thought to be a multifactorial defect of midline mesoderm/endoderm development around the 4th gestational week. Rare familial recurrence suggests genetic heterogeneity (HOXD13, FANCB, mitochondrial mutations in some). Recurrence risk in subsequent pregnancies is generally <5%.

VACTERL is an association, not a syndrome: no unifying mechanism, just statistical co-occurrence of three or more component defects.

Diagnosis requires ≥3 of the following 6 components:

  • Vertebral defects: hemivertebrae, butterfly vertebrae, sacral agenesis (~70%)
  • Anal atresia (~55%)
  • Cardiac defects: VSD most common, also TOF, ASD (~75%)
  • Tracheoesophageal fistula with Esophageal atresia (~70%)
  • Renal anomalies: agenesis, dysplasia, reflux (~50%)
  • Limb anomalies: radial ray defects (absent thumb, hypoplastic radius) (~50%)

Single umbilical artery is a soft marker, not a criterion.

  • Clinical (≥3 cardinal components on physical exam + imaging)
  • Echocardiogram, renal ultrasound, vertebral imaging, limb radiographs: full workup once one component is identified
  • Rule out mimics with chromosomal/genetic testing: karyotype, CMA, FANCB (X-linked), trio exome considered if multiple anomalies are atypical
  • Fanconi anemia must be excluded via chromosome breakage study (DEB/MMC); it shares overlapping radial ray, renal, and cardiac findings, but Fanconi adds bone marrow failure and cancer risk
  • Fanconi anemia: see above; required to exclude
  • CHARGE syndrome: coloboma, choanal atresia, ear anomalies; CHD7
  • Townes-Brocks syndrome: anal atresia + ear + radial ray; SALL1
  • Feingold syndrome: TEF + microcephaly + brachymesophalangy; MYCN
  • 22q11.2 deletion: cardiac defect + characteristic facies + immune findings
  • Surgical repair of correctable anomalies (TEF/EA in first days; anal atresia; cardiac repair as indicated)
  • Renal replacement if bilateral severe disease
  • Spine and limb orthopedic management long-term
  • Developmental support: most have normal cognition, but multiple surgeries and chronic illness affect schooling
  • Genetic counseling: sporadic, low recurrence; offer prenatal imaging in subsequent pregnancies

The acronym IS the diagnostic checklist: Vertebral, Anal, Cardiac, Tracheoesophageal, Esophageal, Renal, Limb. Three or more = association. Always exclude Fanconi anemia: it shares the radial ray + cardiac + renal phenotype.

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