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A 3-year-old with progressive cerebellar ataxia is noted to have oculocutaneous telangiectasias. He has had recurrent sinopulmonary infections. Labs show elevated AFP, low IgA, and lymphopenia. A chest CT is avoided due to radiation sensitivity.

AR; ATM (ataxia-telangiectasia mutated, a serine/threonine kinase involved in DNA double-strand break repair)

  • ATM heterozygous carriers: increased breast cancer risk (~2x; ATM is a moderate-penetrance breast cancer gene)

Neurological:

  • Progressive cerebellar ataxia (onset age 1-4 years, wheelchair-bound by adolescence)
  • Oculomotor apraxia
  • Dysarthria, choreoathetosis

Telangiectasias:

  • Conjunctival and cutaneous (appear age 3-6 years)

Immunodeficiency:

  • Variable T and B cell deficiency
  • Low IgA, IgG subclass deficiency
  • Recurrent sinopulmonary infections

Cancer predisposition:

  • Lymphoma and leukemia (especially in childhood)
  • Increased risk of solid tumors in adulthood
  • Radiation sensitivity: avoid unnecessary X-rays and CT scans

Lab findings:

  • Elevated serum AFP (~95%)
  • Elevated chromosomal breakage (diagnostic test)
  • Elevated serum AFP (present in ~95%) plus low or absent IgA and IgG subclasses supports the diagnosis in a child with ataxia and telangiectasias
  • Radiosensitivity assays and increased chromosomal breakage (including translocations involving chromosomes 7 and 14) on irradiated lymphocytes
  • Absent or reduced ATM protein on immunoblot; ATM sequence and deletion/duplication analysis confirms the diagnosis and enables carrier and prenatal testing
  • Avoid ionizing radiation (X-rays, CT scans)
  • Immunoglobulin replacement for severe immunodeficiency
  • Aggressive treatment of pulmonary infections
  • Cancer surveillance
  • Physical and occupational therapy for ataxia
  • No curative treatment; median survival ~25 years

The name of the disease is very helpful here:

  • Patients present with ataxia (loss of balance) and telangiectasias (vessels on different surfaces of the body)
  • The gene involved is ATM = Ataxia Telangiectasia, Mutated.