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Chronic granulomatous disease (CGD)

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A boy has recurrent abscesses (skin, liver, lungs) and lymphadenitis. Cultures grow catalase-positive organisms (Staph aureus, Aspergillus). DHR flow cytometry is abnormal.

XLR (CYBB, 70%) or AR (CYBA, NCF1, NCF2, NCF4)

  • NADPH oxidase deficiency
  • Recurrent infections with catalase-positive organisms (Staph, Serratia, Aspergillus, Nocardia)
  • Abscesses (skin, liver, lung, lymph nodes)
  • Granuloma formation
  • Inflammatory complications (GI, GU obstruction)
  • Abnormal DHR or NBT test
  • Dihydrorhodamine (DHR123) flow cytometry: measures the oxidative burst; the more sensitive and quantitative first-line functional test
  • Nitroblue tetrazolium (NBT) slide test: older qualitative assay; neutrophils fail to reduce dye to blue formazan
  • Confirmatory molecular testing of CYBB, CYBA, NCF1, NCF2, NCF4 to define genotype and inheritance
  • Carrier testing of at-risk female relatives (X-linked CYBB shows a mosaic/bimodal DHR pattern)
  • Prophylactic antibiotics/antifungals, interferon-gamma, HSCT

The name is descriptive. Look for a patient with multiple chronic infections.

Patients may have acne-like bumps on their skin (granulomas), which reflect localized areas of inflammation. These inflammatory "bumps" can also be found in the internal organs (lungs, lymph nodes, bone).

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