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A 45-year-old presents with iron-deficiency anemia. Colonoscopy reveals 30 adenomatous polyps and a colorectal adenocarcinoma. Family history shows no affected parents but two affected siblings. Genetic testing reveals biallelic MUTYH pathogenic variants.

AR; MUTYH (base excision repair: repairs oxidative DNA damage, specifically 8-oxoguanine)

  • Biallelic variants required for full phenotype
  • Two common European founder variants: Y179C and G396D
  • Monoallelic carriers: modestly increased CRC risk (unclear if clinically actionable)
  • Somatic signature: excess G:C→T:A transversions
  • 20-100 adenomatous polyps (attenuated polyposis phenotype)
  • CRC risk 43-100% without surveillance
  • Later onset than classic FAP (typically 40s-50s)
  • Duodenal adenomas/cancer risk
  • Autosomal recessive: often no family history in parents (horizontal pattern in siblings)
  • MUTYH full gene sequencing
  • Consider in patients with 10-100 adenomatous polyps, especially if APC-negative
  • Consider in early-onset CRC with somatic G:C→T:A signature
  • Colonoscopy every 1-2 years starting age 25-30
  • Upper endoscopy every 3-5 years for duodenal surveillance
  • Colectomy if polyp burden unmanageable by polypectomy
  • Genetic counseling for siblings (25% recurrence risk)

MUTYH = base excision repair (BER): You only need to know the "BER" (bare) minimum about BER: MUTYH is the only well-known disease gene for base excision repair.

MAP is the AR polyposis syndrome: Unlike FAP (AD, APC) and Lynch (AD, MMR), MAP requires biallelic variants. No affected parents, horizontal (sibling) pattern: think AR inheritance when you see multiple affected siblings with polyps.

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