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A 3-year-old has tall stature (well above the 97th percentile), macrocephaly, and a broad forehead with hypertelorism, large ears, and a small chin. The fingers stay flexed at rest (camptodactyly). Bone age is advanced by several years. Development is mildly delayed.

  • EZH2 (chromosome 7q36), the catalytic subunit of the PRC2 polycomb repressive complex
  • Autosomal dominant
  • Most cases de novo
  • Predominantly missense variants clustered in or near the catalytic SET domain (the precise functional consequence is debated)
  • Pre- and postnatal overgrowth, tall stature
  • Macrocephaly with broad forehead and prominent occiput
  • Hypertelorism, large/low-set ears, retrognathia (small lower jaw), almond-shaped eyes
  • Camptodactyly of fingers; deep-set nails; broad thumbs in some
  • Advanced bone age (often by several years)
  • Intellectual disability variable, usually mild to moderate
  • Hypertonia in infancy (contrasts with Sotos, which has hypotonia)
  • Hoarse / low-pitched cry
  • Increased risk of neoplasia in some series (neuroblastoma, leukemia, lymphoma); absolute risk is low but surveillance is sometimes considered
  • Clinical suspicion in tall, macrocephalic child with characteristic face and advanced bone age
  • EZH2 sequencing
  • If negative and overgrowth syndrome still suspected: panel testing covering NSD1 (Sotos), DNMT3A (Tatton-Brown-Rahman), NFIX (Malan), HIST1H1E (Rahman), exome
  • Developmental support, occupational therapy for camptodactyly
  • Monitor growth trajectory
  • Cardiac screening at diagnosis
  • Surveillance for neoplasia is debated; individualize based on family history

"Weaver = Way Exceeds AVERage height/HC." The word "Weaver" itself contains the clinical phenotype: Way Exceeds AVERage head circumference and height. The two body parameters that are well above average are the diagnostic anchors.

"Wide-spaced Eyes." Hypertelorism is part of the Weaver gestalt; the W also stands for the Wide eyes.

"EZH2 = EyeZ + (EZ)H²." Decode the gene name as a phenotype mnemonic: Eyes (hypertelorism) plus H × H (Height and Head circumference both raised). Three of the most consistent Weaver features encoded in the gene symbol.

Weaver vs Sotos (the two textbook overgrowth syndromes to distinguish):

FeatureSotos (NSD1)Weaver (EZH2)
Tone in infancyHypotoniaHypertonia
ForeheadFrontal bossing, dolichocephalicBroad, prominent occiput
HandsLarge, softCamptodactyly
CryNormalLow-pitched, hoarse
Bone ageAdvancedAdvanced (often more)
Polycomb biologyNSD1 adds H3K36meEZH2 adds H3K27me (PRC2)

"EZH2 = epigenetic, fingers bent": EZH2 is a histone methyltransferase, and the camptodactyly is the bedside finding that pulls Weaver away from Sotos.

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