StudyRareStudyRare
Log in to add personal notes on this page.

A Southeast Asian couple has a stillborn infant with hydrops fetalis. Hemoglobin electrophoresis shows only Hb Bart's (γ4). The parents are both α-thalassemia trait carriers with --/αα genotype.

AR; HBA1 and HBA2 (chromosome 16)

  • Usually deletions

Types (by # of functioning α genes):

ConditionGenotypePhenotype
Silent carrier-α/ααNormal
α-thal trait--/αα or -α/-αMild microcytic anemia
HbH disease--/-αModerate hemolytic anemia, HbH (β4)
Hb Bart's hydrops--/--Lethal, hydrops fetalis, Hb Bart's (γ4)
  • --/αα (cis deletions) common in Southeast Asian populations → risk for Bart's hydrops
  • -α/-α (trans deletions) common in African populations → lower risk for Bart's hydrops
  • CBC shows microcytic, hypochromic anemia (low MCV) with normal or elevated RBC count and normal iron studies (distinguishes from iron deficiency)
  • Hemoglobin electrophoresis or HPLC: HbH (β4) in HbH disease, Hb Bart's (γ4) at birth or in hydrops; HbA2 is normal or low (unlike beta-thalassemia)
  • HBA1/HBA2 deletion analysis (MLPA or gap-PCR) confirms genotype and identifies cis (--/αα) vs trans (-α/-α) for reproductive risk
  • Carrier testing and prenatal diagnosis indicated when both partners carry α-globin deletions
  • Silent carrier and trait: no treatment; genetic counseling and avoidance of unnecessary iron supplementation
  • HbH disease: folic acid, intermittent transfusion during hemolytic or aplastic crises, splenectomy in selected cases, iron monitoring
  • Hb Bart's hydrops: usually lethal in utero; rare survivors require intrauterine transfusion and lifelong transfusion support
  • HSCT is potentially curative for transfusion-dependent disease

Hb Barts = Bad. Hb Barts is seen in an unborn Baby with fetal hydrops due to 4-gene deletion of alpha-thalassemia.

The letter "H" in HbH has 4 points. Represents the beta-globin tetramer.

Alpha is the most "social" Hb. Alpha-globin pairs with all other globin chains (β, γ, δ), which is why alpha-thalassemia affects multiple hemoglobin types.

Hemoglobinopathies and hemoglobin electrophoresis
Hemoglobinopathies and hemoglobin electrophoresis