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An infant with macrocephaly and hypotonia develops progressive spasticity, visual impairment, and seizures. MRI shows diffuse white matter involvement. N-acetylaspartic acid is elevated in urine.

AR; ASPA (aspartoacylase)

  • Common in Ashkenazi Jewish population
  • Leukodystrophy (spongiform white matter degeneration)
  • Macrocephaly (progressive)
  • Hypotonia → spasticity
  • Severe developmental regression
  • Visual impairment, optic atrophy
  • Elevated N-acetylaspartic acid (NAA) in urine, blood, CSF
  • MRI: diffuse white matter changes, subcortical U-fiber involvement

Carrier Screening: Included in Ashkenazi Jewish panel

  • Not on RUSP; suspected clinically (macrocephaly, leukodystrophy on MRI)
  • Markedly elevated N-acetylaspartic acid (NAA) on urine organic acids; elevated NAA peak on MR spectroscopy
  • Confirmation: deficient aspartoacylase activity or biallelic ASPA variants
  • Supportive only: no disease-modifying therapy
  • Seizure control, feeding/nutrition support, management of spasticity, physical therapy
  • ASPA gene therapy under investigation

CaNAAvan has elevated NAA: Canavan disease is diagnosed by elevated N-acetylaspartic acid (NAA) on urine organic acids and MR spectroscopy.

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