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A 40-year-old man presents with a 3-year history of progressive unsteadiness, slurred speech, and difficulty with fine motor tasks. His father had similar symptoms starting at age 50 and is now wheelchair-bound. Neurologic exam reveals gait and limb ataxia, dysarthria, and nystagmus. Brain MRI shows cerebellar atrophy.

Hereditary ataxias are a genetically heterogeneous group

  • Autosomal dominant: Spinocerebellar ataxias (SCAs); most involve trinucleotide repeat expansions
  • Autosomal recessive: Friedreich ataxia (most common), ataxia-telangiectasia, others
  • X-linked: Fragile X-associated tremor/ataxia syndrome (FXTAS)
  • Mitochondrial: NARP, some MERRF presentations

Autosomal dominant ataxias (SCAs):

  • 40+ subtypes identified (SCA1-48+)
  • Most common: SCA1, SCA2, SCA3 (Machado-Joseph, most common worldwide), SCA6, SCA7
  • CAG (polyglutamine) repeat expansions in SCA1, 2, 3, 6, 7
  • Adult onset typically (30s-50s)
  • Anticipation: earlier onset and increased severity in successive generations
  • Key distinguishing features:
    • SCA2: slow saccades
    • SCA3: "bulging eyes," dystonia, peripheral neuropathy
    • SCA6: pure cerebellar, later onset, more benign
    • SCA7: retinal degeneration (pigmentary macular dystrophy)

Autosomal recessive ataxias:

  • Friedreich ataxia: most common hereditary ataxia overall. GAA repeat in FXN. Onset <25 years. Cardiomyopathy, scoliosis, diabetes. Absent reflexes + Babinski.
  • Ataxia-telangiectasia: ATM gene. Childhood onset. Telangiectasias, immunodeficiency, cancer predisposition, elevated AFP. Radiosensitivity.
  • Ataxia with oculomotor apraxia types 1 and 2
  • Autosomal recessive spastic ataxia of Charlevoix-Saguenay (ARSACS)
  • Clinical evaluation: onset, progression, family history, associated features
  • Brain MRI: cerebellar atrophy pattern
  • Trinucleotide repeat testing for SCAs (targeted or panel)
  • FXN GAA repeat analysis for Friedreich ataxia
  • AFP level if ataxia-telangiectasia suspected
  • Multi-gene panel or exome sequencing for unexplained ataxia
  • EMG/NCS to evaluate peripheral neuropathy
  • No disease-modifying therapy for most SCAs
  • Omaveloxolone (Skyclarys): FDA approved for Friedreich ataxia (Nrf2 activator)
  • Physical therapy, occupational therapy, speech therapy
  • Fall prevention and home safety modifications
  • Cardiac surveillance for Friedreich ataxia (echocardiogram, ECG)
  • Genetic counseling: AD ataxias have 50% recurrence risk; counseling regarding anticipation and predictive testing in at-risk relatives
  • Avoidance of radiation exposure in ataxia-telangiectasia

"SCA7 = Seven = Seen": Drop the "V" from "Seven" to get "Seen." SCA7 is the ataxia uniquely associated with vision loss (retinal degeneration / pigmentary macular dystrophy).

SCA3 (Machado-Joseph) is the most common SCA worldwide: It is uniquely associated with "bulging eyes" and dystonia.

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