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Hereditary fructose intolerance

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An infant develops vomiting, hypoglycemia, and liver dysfunction after introduction of fruit/juice. Symptoms resolve when fructose is removed.

AR; ALDOB (aldolase B)

  • Symptoms after fructose/sucrose/sorbitol exposure
  • Hypoglycemia, vomiting, hepatomegaly
  • Aversion to sweets (protective)
  • Avoid IV solutions containing fructose
  • Not on newborn screening; suspect from symptoms (vomiting, hypoglycemia, hepatomegaly) triggered by fructose/sucrose/sorbitol exposure
  • Acute exposure causes hypoglycemia, hypophosphatemia, hyperuricemia, lactic acidosis, and abnormal liver/renal function
  • Confirmatory ALDOB molecular testing (preferred); the fructose tolerance test is diagnostic but hazardous and largely replaced by genetic testing
  • Reduced aldolase B activity on liver biopsy if molecular testing is inconclusive
  • Fructose/sucrose/sorbitol-free diet

"ALdo B = A Liver enzyme": aldolase B is only expressed in the liver, which is why hepatomegaly and liver damage dominate. Fructose-1-phosphate accumulates and traps phosphate.

"He-Re-di-tary" = Hepatic, Renal function is Fruct'd up: liver and kidney are both affected.

Low "FuSS" diet: avoid Fructose, Sucrose (glucose + fructose), and Sorbitol (converted to fructose). "Fruit-toSS": toss out foods with fructose, sucrose, and sorbitol.

"Kinase = kinder": fructokinase (KHK) deficiency is essential fructosuria, a benign condition with isolated fructosuria. HFI (aldolase B) causes liver and kidney damage. Same pattern in the galactose pathway: galactokinase (GALK1) deficiency = cataracts only vs classic GALT galactosemia = severe. The first kinase step is the kinder deficiency in both sugar pathways.

This table lists the four disorders of fructose metabolism: "Fruit Sorbet Is Healthy". Fructose-1,6-bisphosphatase deficiency, Sorbitol dehydrogenase deficiency, Essential fructosuria (benign), and Hereditary fructose intolerance.

Four disorders of fructose metabolism: "Fruit Sorbet Is Healthy". Fructose-1,6-bisphosphatase deficiency, Sorbitol dehydrogenase deficiency, essential fructosuria, and hereditary fructose intolerance
Four disorders of fructose metabolism: "Fruit Sorbet Is Healthy". Fructose-1,6-bisphosphatase deficiency, Sorbitol dehydrogenase deficiency, essential fructosuria, and hereditary fructose intolerance

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