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A 3-month-old male infant presents with seizures, hypotonia, and failure to thrive. He has sparse, kinky, colorless hair ("steel wool"). Labs show low serum copper and ceruloplasmin.

XLR; ATP7A (copper transporter)

  • Sparse, kinky, hypopigmented hair (pili torti)
  • Progressive neurodegeneration, seizures
  • Connective tissue abnormalities (bladder diverticula, vascular tortuosity)
  • Hypothermia
  • Low copper and ceruloplasmin

Death: Usually by age 3 years

  • Low serum copper and ceruloplasmin in an affected male infant (note: low normal in healthy newborns, so interpret with caution)
  • Confirm with ATP7A sequencing/deletion analysis; plasma and CSF catecholamine ratios can support the diagnosis
  • Hair microscopy shows pili torti; brain MRI/MRA may show vascular tortuosity and neurodegeneration
  • Subcutaneous copper (if started early, may improve outcomes)

"Men get Menkes": Menkes disease is X-linked recessive, primarily affecting males.