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Noonan syndrome with multiple lentigines (NSML, formerly LEOPARD)

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A child with multiple café-au-lait macules and dark lentigines covering the trunk has hypertrophic cardiomyopathy on echo, mild hypertelorism, and sensorineural deafness. Pulmonary stenosis was suspected but echo shows obstructive HCM instead.

AD; mostly PTPN11 (~85%, but catalytically inactive (loss-of-function) variants of SHP2 phosphatase activity, distinct from Noonan's gain-of-function mutations), with RAF1 and BRAF in a minority. Same RAS-MAPK pathway as Noonan, opposite mutation effect on PTPN11.

  • Lentigines: multiple, dark, scattered (not photoexposed-only)
  • ECG conduction abnormalities
  • Ocular hypertelorism
  • Pulmonary stenosis (less common than Noonan; HCM more common)
  • Abnormal genitalia (cryptorchidism)
  • Retardation of growth (short stature)
  • Deafness (sensorineural)

Hypertrophic cardiomyopathy in NSML is frequent and clinically dominant, distinct from Noonan, where pulmonary stenosis is the headline cardiac finding.

Clinical (lentigines + cardiac findings + facial features) plus PTPN11/RAF1/BRAF sequencing. Café-au-lait macules can mimic NF1; lentigines are the differentiating feature (sharper, darker, no neurofibromas).

  • Noonan syndrome: same pathway, similar facies, but pulmonary stenosis dominates and lentigines are absent.
  • NF1: café-au-lait + neurofibromas + Lisch nodules; lentigines NSML are histologically different.
  • Carney complex: lentigines + cardiac myxomas + endocrine tumors.
  • Cardiology surveillance with serial echo (HCM progression)
  • Audiology (sensorineural hearing loss in ~25%)
  • Growth monitoring; growth hormone considered case-by-case
  • Genetic counseling: autosomal dominant, ~50% recurrence

LEOPARD spots map to the seven cardinal features above. The animal is hard to forget; remember the modern name (NSML) is preferred because the legacy acronym is phasing out of clinical use.

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