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Retinitis pigmentosa

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A 25-year-old man reports difficulty seeing at night since his teens, worsening to "tunnel vision" over the past 5 years; he is now bumping into objects in his peripheral field. Fundoscopy shows the classic triad of bone-spicule pigmentation in the mid-periphery, attenuated retinal vessels, and a waxy-pale optic disc. Full-field ERG shows severely reduced rod responses with relatively preserved cone responses, confirming a rod-cone dystrophy pattern.

Retinitis pigmentosa (RP) is the prototypical inherited rod-cone dystrophy: primary degeneration of rod photoreceptors, with cones following later. "RP" by convention refers to non-syndromic disease; syndromic RP (RP as part of a multi-system genetic disorder) is a separate clinical category.

CategoryKey examples
Non-syndromic RPThis entry
Syndromic RPUsher syndrome (RP + sensorineural hearing loss), Bardet-Biedl syndrome (RP + obesity + polydactyly + ID + renal anomalies), Refsum disease (RP + anosmia + ataxia + elevated phytanic acid), Alström syndrome, Cohen syndrome, neuronal ceroid lipofuscinoses

Extremely heterogeneous: >80 genes; all Mendelian inheritance patterns plus mitochondrial.

InheritanceApproximate frequencyCommon genes
AD~30-40%RHO (rhodopsin, most common AD gene), PRPH2, RP1, PRPF31, IMPDH1, NR2E3
AR~50-60%USH2A (also Usher type 2, same gene different phenotype), RPE65 (also Leber congenital amaurosis), EYS, CRB1, CNGA1, PDE6A/B, ABCA4
X-linked~10-15%RPGR (most common XL form, especially the ORF15 mutation hotspot), RP2
MitochondrialrareConsider in maternal-pattern pedigrees; usually with broader mitochondrial features
DigenicrarePRPH2 + ROM1 classic example

Key counseling pearls:

  • USH2A pleiotropy: the same USH2A variants can cause non-syndromic RP or Usher type 2 (RP + congenital hearing loss). Audiologic evaluation is mandatory at diagnosis of USH2A RP.
  • RPGR XL pattern: affected males have severe early-onset RP; carrier females show variable findings on exam (tapetal-like reflex, sectoral retinopathy) due to X-inactivation and may have meaningful visual symptoms.
  • RPE65 biallelic disease is now treatable. See Management.

Diverse molecular pathways converge on rod photoreceptor death:

  • Phototransduction defects (RHO, PDE6A/B, CNGA1)
  • Visual cycle / RPE function (RPE65, LRAT)
  • Outer segment structure (PRPH2, ROM1, RP1)
  • Cilium / connecting cilium (RPGR, USH2A, CEP290)
  • Splicing factors (PRPF31, PRPF8, PRPF3), surprisingly retina-specific despite ubiquitous expression

Once rod death is established, secondary cone death occurs partly via loss of rod-derived cone viability factor (RdCVF).

Symptoms (in order of typical progression):

  1. Nyctalopia (night blindness): usually the first symptom, often in childhood/adolescence
  2. Mid-peripheral visual field loss"tunnel vision" over years
  3. Eventual loss of central vision
  4. Photopsias, slow dark adaptation

Fundus (classic triad):

  • Bone-spicule pigmentation: black perivascular pigment clumping in the mid-periphery (RPE migration)
  • Attenuated retinal vessels ("threadlike" arterioles)
  • Waxy-pale optic disc (reflects long-standing RGC stress)

Other findings:

  • Posterior subcapsular cataract (common in adults; often a treatable cause of acute visual decline)
  • Cystoid macular edema (CME): treatable; topical/oral CAIs help
  • Refractive error (myopia common)
  • Vitreous cells/pigment

Functional testing:

  • Full-field ERG: reduced/extinguished rod responses early, cone responses follow
  • Visual field testing: mid-peripheral ring scotoma → progressive constriction
  • OCT: thinning of the outer nuclear layer with preservation of central ellipsoid zone until later
  • Fundus autofluorescence (FAF): hyperautofluorescent ring around the macula at the boundary of preserved photoreceptors
  • Clinical recognition + ERG → multigene panel sequencing (best yield) covering all RP genes plus syndromic mimics
  • Audiology evaluation (mandatory; Usher syndrome considerations)
  • Renal/metabolic workup if syndromic features suggest BBS, Senior-Løken, etc.
  • For females with isolated RP, consider RPGR carrier testing (cascade implications)

Disease-modifying:

  • Voretigene neparvovec (Luxturna): FDA-approved subretinal AAV2 gene therapy for biallelic RPE65-related retinal dystrophy (RP/LCA spectrum). The first FDA-approved gene therapy for an inherited disease and a major reason molecular diagnosis matters in RP.
  • Multiple AAV-based and antisense oligonucleotide therapies in trials for other genotypes (RHO, USH2A, RPGR, CEP290)
  • Retinal prostheses (Argus II historically, newer optogenetic approaches in trials)

Symptomatic / supportive:

  • Vitamin A palmitate: modestly slows ERG decline in some adult RP (NOT in Stargardt disease / ABCA4, and avoid in pregnancy)
  • DHA supplementation, low-glycemic diet (modest evidence)
  • UV protection
  • Cataract extraction when visually significant
  • CME treatment (topical brinzolamide, oral acetazolamide, intravitreal steroids)
  • Low-vision rehabilitation, orientation/mobility, vocational support
  • Genetic counseling and cascade testing based on identified inheritance pattern
  • Cone-rod dystrophy: central vision loss precedes peripheral; cones affected first
  • Choroideremia: XL, CHM; scalloped chorioretinal atrophy
  • Gyrate atrophy: AR, OAT; ornithine elevated; arginine-restricted diet
  • Vitamin A deficiency: acquired phenocopy with night blindness; reversible
  • Drug-induced retinopathy: chloroquine, thioridazine; medication history

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