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A 6-month-old of Ashkenazi Jewish ancestry has developmental regression, exaggerated startle response, and cherry-red spot on fundoscopy. Hexosaminidase A is deficient.

AR; HEXA (hexosaminidase A)

  • Common in Ashkenazi Jewish, French Canadian, Cajun populations
  • GM2 ganglioside accumulation
  • Normal at birth, regression begins 3-6 months
  • Cherry-red spot on macula
  • Exaggerated startle response
  • Progressive neurodegeneration, blindness, seizures
  • Macrocephaly
  • Death by 4-5 years

Carrier Screening: Enzyme assay or DNA testing for at-risk populations

  • Deficient hexosaminidase A enzyme activity in serum or leukocytes (with normal/elevated total hexosaminidase, reflecting preserved Hex B)
  • HEXA molecular testing confirms the diagnosis and resolves pseudodeficiency alleles that lower enzyme activity without causing disease
  • Cherry-red macula on fundoscopy supports the clinical picture
  • No disease-modifying therapy; supportive and palliative care
  • Anticonvulsants for seizures, nutritional support for dysphagia, secretion management
  • Genetic counseling and carrier screening for at-risk populations; prenatal/preimplantation testing options

tAy sAchs = hexA: Tay-Sachs is caused by deficiency of hexosaminidase A (the "A" appears in both "tAy" and "sAchs"). Compare with Sand-hoff = hexB ("get the Sand off at the Beach").

Tay-Sachs has a Typical Spleen: no hepatosplenomegaly (vs. Niemann-Pick, which has a Massive sPleen). Both have a cherry-red spot on the macula.

GM2 ganglioside: 2 words, 2 syllables (Tay-Sachs): GM2. "Ganglioside" makes you think of ganglia/neurons: only neurons are affected. Death by age 4 years; exaggerated startle response ("Taylor Swift is a star").