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Congenital contractural arachnodactyly (CCA/Beals syndrome)

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A newborn has long, slender fingers (arachnodactyly), multiple joint contractures, and "crumpled" ears. The baby has a Marfanoid appearance but no lens dislocation.

AD; FBN2 (fibrillin-2)

  • Related to Marfan syndrome (FBN1 = fibrillin-1)
  • Arachnodactyly
  • Congenital contractures (knees, elbows, hips, fingers) - often improve with time
  • "Crumpled" or folded ears (characteristic)
  • Marfanoid body habitus
  • Kyphoscoliosis
  • NO lens dislocation (unlike Marfan)
  • Minimal cardiovascular involvement
  • Clinical: arachnodactyly plus congenital contractures plus the characteristic crumpled/folded ears in a marfanoid infant
  • Distinguish from Marfan syndrome: contractures and crumpled ears favor CCA; ectopia lentis and significant aortic dilation favor Marfan
  • Baseline echocardiogram to assess for aortic root dilation (usually mild and nonprogressive)
  • FBN2 sequencing confirms
  • Physical therapy and stretching for contractures, which often improve over time
  • Orthopedic surveillance and management of kyphoscoliosis
  • Periodic echocardiographic monitoring of the aortic root

BEALS = BEnt And Long, Skinny fingers and toes.

Fibrillin Two (FBN2) affects Fingers and Twoes (toes).

FBN2 "Pro-two-ects" against aortic root dilation: aortic root dilation is less severe in CCA than in Marfan syndrome (FBN1).

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