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NARP (neuropathy, ataxia, retinitis pigmentosa)

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A young adult with developmental delay has progressive ataxia, peripheral neuropathy, and night blindness. Retinitis pigmentosa is found on fundoscopy.

Maternal (mtDNA); MT-ATP6 m.8993T>G or T>C

  • Same gene as some Leigh syndrome cases
  • Higher mutant load (>90%) → Leigh syndrome
  • Lower mutant load (70-90%) → NARP
  • Peripheral neuropathy (sensory)
  • Cerebellar ataxia
  • Retinitis pigmentosa
  • Developmental delay/cognitive impairment
  • Proximal muscle weakness
  • Seizures (some)
  • Overlaps with Leigh syndrome at high heteroplasmy
  • Targeted mtDNA testing for MT-ATP6 m.8993T>G or T>C, with heteroplasmy quantification (severity tracks mutant load)
  • Fundoscopy confirms retinitis pigmentosa; brain MRI may show cerebellar/brainstem changes
  • Unlike many mitochondrial disorders, muscle biopsy typically does not show ragged red fibers
  • Largely supportive (no disease-modifying therapy): low-vision support, physical therapy for ataxia, anticonvulsants for seizures
  • Maternally inherited (mtDNA): all offspring of an affected mother are at risk, and heteroplasmy makes recurrence severity unpredictable

NARP = the diagnosis: the name itself is the mnemonic: Neuropathy, Ataxia, Retinitis Pigmentosa. All three cardinal features are in the name.

Same gene, different load: MT-ATP6 mutations at m.8993 show lower heteroplasmy (70-90%) causing NARP, while higher mutant load (>90%) causes the more severe Leigh syndrome.

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