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A newborn male has 2-3 toe syndactyly, ambiguous genitalia (undervirilization), microcephaly, and cleft palate. 7-dehydrocholesterol is markedly elevated.

AR; DHCR7 (7-dehydrocholesterol reductase)

  • Final step of cholesterol biosynthesis
  • 2-3 toe syndactyly (highly characteristic)
  • Microcephaly, intellectual disability
  • Genital anomalies (males - hypospadias to female external genitalia)
  • Cleft palate, micrognathia
  • Ptosis, anteverted nares
  • Congenital heart defects
  • Behavioral problems (autism, self-injury)
  • Elevated 7-dehydrocholesterol (7-DHC); low cholesterol
  • Cholesterol supplementation (limited efficacy)

"SLOppy Joes are full of Cholesterol": SLOS is a cholesterol synthesis defect. DHCR7 catalyzes the last step: 7-dehydrocholesterol to cholesterol.

Patients are "SLLOW.": Short stature, Limb defects (polydactyly/syndactyly, proximal thumb), Learning disability + microcephaly, Openings issues (hypospadias, cleft palate), W looks like 2 digits (extra or fused toes, i.e. 2-3 syndactyly).

Sonic hedgehog is fast, the opposite of "SLO": cholesterol is essential for hedgehog signaling (sonic hedgehog mediates midline development, explaining holoprosencephaly and midline defects in severe cases).