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Cerebrotendinous xanthomatosis

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A young adult with intellectual disability has bilateral cataracts and progressive ataxia. MRI shows white matter abnormalities. Serum cholestanol is elevated.

AR; CYP27A1 (sterol 27-hydroxylase)

  • Defective bile acid synthesis → cholestanol accumulation
  • Juvenile cataracts (often first sign)
  • Progressive neurological dysfunction (ataxia, dementia, spasticity)
  • Tendon xanthomas
  • Chronic diarrhea (childhood)
  • Treatable if diagnosed early
  • Elevated serum cholestanol; genetic testing
  • Chenodeoxycholic acid (bile acid replacement) - prevents progression if started early

CTX = Cataracts + Tendon Xanthomas: the two hallmark findings, derived directly from the abbreviation.

"CanT Xcrete bile acids": CTX is a bile acid synthesis defect (CYP27A1). Cholesterol and cholestanol accumulate in brain ("cerebro-") and tendons ("-tendinous").

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